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Fujita, Yuya; Sato, Shuzo; Matsumoto, Haruki; Temmoku, Jumpei; Yashiro-Furuya, Makiko; Matsuoka, Naoki; Asano, Tomoyuki; Yokose, Kohei; Yoshida, Shuhei; Ohtsuka, Mikio; Watanabe, Hiroshi; Migita, Kiyoshi
The Tohoku Journal of Experimental Medicine, 2021, Letnik: 255, Številka: 4Journal Article
A 38-year-old male was admitted to our hospital for arthralgia, fever, skin rash, and purpura. He was diagnosed as having adult-onset Still’s disease (AOSD) based on Yamaguchi’s criteria. Skin biopsy revealed immunoglobulin A (IgA) vasculitis. He was also found to have anti-cyclic citrullinated peptide (CCP) antibody-positive inflammatory arthritis on a shoulder joint, however he did not fulfill classification criteria for rheumatoid arthritis. Elevated serum cytokine such as serum IL-18 supported the diagnosis of AOSD. His symptoms improved with 40 mg of prednisolone plus cyclosporin A (200 mg/day). Two years after hospitalization, AOSD was relapsed with pleurisy and hyperferritinemia. Finally, he was diagnosed with multicyclic systemic type of AOSD complicated by IgA vasculitis and seropositivity of anti-CCP antibody. Clinicians need to consider the complication of multiple rheumatic diseases, even if the disease-specific autoantibody is positive.
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JCR | SNIP | JCR | SNIP | JCR | SNIP | JCR | SNIP |
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in: SICRIS
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